A 60-year-old female patient was referred by an outside oral and maxillofacial surgeon
for evaluation of a left posterior mandibular “lesion.” The patient estimated that
she had first experienced pain associated with the left mandibular posterior teeth
approximately 6 months before presentation. She also experienced progressive difficulty
with mastication on the left side. She was seen by her general dentist and was referred
to an oral surgeon for extraction of the left mandibular posterior teeth due to periodontally
compromised dentition. After extraction of the left posterior molars, the surgical
site did not appear normal. This prompted an incisional biopsy of the left mandible.
The patient was then referred to our institution for further management.
To read this article in full you will need to make a payment
Purchase one-time access:
Academic & Personal: 24 hour online accessCorporate R&D Professionals: 24 hour online accessOne-time access price info
- For academic or personal research use, select 'Academic and Personal'
- For corporate R&D use, select 'Corporate R&D Professionals'
Subscribe:
Subscribe to Oral Surgery, Oral Medicine, Oral Pathology and Oral RadiologyAlready a print subscriber? Claim online access
Already an online subscriber? Sign in
Register: Create an account
Institutional Access: Sign in to ScienceDirect
REFERENCES
- Langerhans cell histiocytosis.N Engl J Med. 1987; 316: 747-748
- Langerhans's cell histiocytosis in old subjects: two rare case reports and review of the literature.Gerodontology. 2012; 29: e1207-e1214
- Langerhans cell histiocytosis: oral/periodontal involvement in adult patients.Oral Dis. 2009; 15: 596-601
- Maxillofacial manifestations of Langerhans cell histiocytosis: a clinical and therapeutic analysis of 10 patients.Oral Oncol. 2003; 39: 687-694
- Radiographic findings in Langerhans’ cell disease affecting the mandible.Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 1995; 79: 251-254
- Primary intraosseous carcinoma: review of the literature and diagnostic criteria.J Oral Maxillofac Surg. 1994; 52: 580-583
- Primary intraosseous odontogenic carcinoma arising in an odontogenic cyst or de novo: a clinicopathologic study of six new cases.Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2006; 101: 194-200
- Primary intraosseous carcinoma of the jaw: pooled analysis of world literature and report of two new cases.Int J Oral Maxillofac Surg. 2001; 30: 349-355
- Preoperative chemoradiotherapy in the management of oral cancer: a review.J Craniomaxillofac Surg. 2008; 36: 75-88
- Metastatic tumors to the jawbones: analysis of 390 cases.J Oral Pathol Med. 1994; 23: 337-341
- Metastatic tumors to the oral cavity: a clinical study of 18 cases.Head Neck Pathol. 2011; 5: 355-358
- Craniofacial metastases: a 20-year survey.J Craniomaxillofac Surg. 2011; 39: 135-137
- Metastatic tumours to the oral region. An overview.Eur J Cancer B Oral Oncol. 1995; 31B: 355-360
- Tumors metastatic to the mandible: analysis of nine cases and review of the literature.J Oral Maxillofac Surg. 1990; 48: 246-251
- Metastatic tumors to the jaws and oral cavity.J Oral Maxillofac Pathol. 2013; 17: 71-75
- Primary intraosseous mucoepidermoid carcinoma of the mandible: radiographic evolution and clinicopathological features.BMJ Case Rep. 2019; 12e224612
- An unusual case of intraosseous mucoepidermoid carcinoma of the mandible: a case report and literature review.Medicine (Baltimore). 2018; 97: e13691
- Intraosseous mucoepidermoid carcinoma of jaws: report of 24 cases.Oral Surg Oral Med Oral Pathol Oral Radiol. 2012; 114: 424-429
- Pattern of care and impact of prognostic factors in the outcome of ameloblastic carcinoma: a systematic review and individual patient data analysis of 199 cases.Eur Arch Otorhinolaryngol. 2017; 274: 3803-3810
- Ameloblastic carcinoma: an analysis of 6 cases with review of the literature.Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2009; 108: 904-913
- Peterson's Principles of Oral and Maxillofacial Surgery.2nd ed. BC Decker, Hamilton, ON, Canada2004
- Maxillofacial osteomyelitis in immunocompromised patients: a demographic retrospective study.J Maxillofac Oral Surg. 2020; 19: 273-282
- Is primary chronic osteomyelitis a uniform disease? Proposal of a classification based on a retrospective analysis of patients treated in the past 30 years.J Craniomaxillofac Surg. 2004; 32: 43-50
- Systematic review of oral manifestations related to hyperparathyroidism.Clin Oral Investig. 2018; 22: 1-27
- Hyperparathyroidism diagnosed due to brown tumors of the jaw: a case report and literature review.J Oral Maxillofac Surg. 2017; 75: 2162-2169
- Dental aspects of hyperparathyroidism.Oral Surg Oral Med Oral Pathol. 1968; 26: 184-189
- Highly aggressive brown tumour of the maxilla as first manifestation of primary hyperparathyroidism.Int J Oral Maxillofac Surg. 2000; 29: 447-449
- Massive osteolysis (acute spontaneous absorption of bone, phantom bone, disappearing bone): its relation to hemangiomatosis.J Bone Joint Surg Am. 1955; 37-A: 985-1004
Romer O. Die Pathologie der Zahne. In: Von Henke F, Lubarsch O., (eds.), Handbuch der speziellen pathologischen Anatomie und Histologie. Vol. 4. Berlin: Springer Verlag; 1924;135-499.
- Histological features and management of a mandibular Gorham disease: a case report and review of maxillofacial cases in the literature.Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2008; 106: e30-e37
- Gorham-Stout disease with involvement of the jaws: a systematic review.Int J Oral Maxillofac Surg. 2019; 48: 1015-1021
- Vanishing bone disease (Gorham-Stout syndrome): a review of a rare entity.World J Orthop. 2014; 5: 694-698
- Massive osteolysis affecting the mandible.Br Dent J. 1966; 120: 538-541
- Seven-year follow-up of vanishing bone disease in a 14-year-old girl.Head Neck. 1993; 15: 352-356
- Craniofacial CT findings of Gorham-Stout disease and generalized lymphatic anomaly.Neuroradiology. 2016; 58: 801-806
- Goham-Stout syndrome, a rare clinical entity and review of literature.Oral Surg Oral Med Oral Pathol Oral Radiol Endod. 2010; 109: e41-e48
- Total mandibular reconstruction for massive osteolysis of the mandible (Gorham-Stout syndrome).Br J Oral Maxillofac Surg. 2005; 43: 166-168
- Gorham-Stout disease: progressive massive osteolysis of the mandible.J Oral Maxillofac Surg Med Pathol. 2016; 28: 147-151
- Mandibular Gorham-Stout disease: a case report and literature review.Medicine (Baltimore). 2017; 96: e8184
- Temporomandibular joint anomalies in pediatric craniofacial Gorham-Stout disease.J Craniomaxillofac Surg. 2018; 46: 1179-1184
- Gorham's disease: a diagnostic challenge.J Oral Maxillofac Pathol. 2014; 18: 411-414
- Observations on massive osteolysis; a review of the literature and report of a case.Radiology. 1958; 71: 28-42
- Fatal progression of gorham disease: a case report and review of the literature.J Oral Maxillofac Surg. 2015; 73: 2352-2360
- Chylothorax in Gorham's syndrome. A common complication of a rare disease.Chest. 1994; 105: 208-213
- Stout disease of the mandible, manubrium and cervical spine presenting as bilateral chylothorax.BMJ Case Rep. 2021; 14e237638
- Chylothorax as a debut form of Gorham-Stout disease.Pulmonology. 2019; 25: 195-197
- A rare case of Gorham-stout syndrome involving the thoracic spine with progressive bilateral chylothorax: a case report.BMC Musculoskelet Disord. 2019; 20: 154
- A new case and review of chylothorax in generalized lymphatic anomaly and Gorham-Stout disease.Lymphology. 2016; 49: 73-84
- Radiation therapy in the treatment of Gorham disease.J Pediatr Hematol Oncol. 2003; 25: 816-817
- Gorham's syndrome: a usually fatal cause of pleural effusion treated successfully with radiotherapy.Thorax. 1996; 51: 1275-1276
- A case of Gorham's disease with chylothorax treated curatively with radiation therapy.Clin Med Res. 2005; 3: 83-86
- Alpha-2b interferon and oral clodronate for Gorham's disease.Lancet. 1997; 350: 1822-1823
- Administration of octreotide for management of postoperative high-flow chylothorax.Ann Vasc Surg. 2007; 21: 90-92
- The successful use of octreotide in the treatment of traumatic chylothorax.Tex Heart Inst J. 2012; 39: 428-430
- Reduction of lymphorrhagia from ruptured thoracic duct by somatostatin.Lancet. 1990; 336: 258
- A prospective study on the role of octreotide in management of chyle fistula neck.Laryngoscope. 2015; 125: 1624-1627
- Systematic management of chyle fistula: the Southwestern experience and review of the literature.Otolaryngol Head Neck Surg. 2000; 122: 31-38
Article info
Publication history
Published online: June 26, 2021
Accepted:
June 21,
2021
Received in revised form:
June 16,
2021
Received:
March 4,
2021
Identification
Copyright
© 2021 Elsevier Inc. All rights reserved.