: In this study, we aimed to review the reported cases of hydatid disease of the bone
in terms of etiology, pathogenesis, and histopathologic, serologic, and radiographic
features, and the management of the disease.
: The present case study reports an extremely rare occurrence of intraosseous hydatid
cysts in the orofacial region, wherein the symptoms or signs of systemic hydatid disease
were absent. We discuss the challenges encountered during the diagnosis and treatment
of osseous hydatidosis, and reviewed articles on osseous hydatidosis, including 97
cases. We also compared the aspects reported in previous cases of mandibular hydatid
cyst with that of the present case.
: Hydatid cysts were found to be present in almost every bone of the skeleton in patients,
with mean age of 39.95 ± 19.67 years (range, 3–76 years). A slight male preference
(58.8%) was observed. A history of rural lifestyle, animal bites, and trauma in the
affected bone was reported. Only five reports on mandibular bone have been published
previously, of which three were primary.
: The presence of hydatid cysts in unusual anatomic locations, mainly due to the lack
of usual presentations and radiographic features, makes differential diagnosis difficult.
The potential risk of anaphylactic shock in susceptible individuals, high recurrence
rate, and the risk of secondary hydatidosis poses diagnostic and surgical challenges.